Skeletal disorders associated with fibroblast growth factor receptor mutations.

Curr Opin Genet Dev

Imperial Cancer Research Fund, London, UK.

Published: June 1997

Mutations in three fibroblast growth factor receptor loci underlie several autosomal dominant skeletal disorders; these include dwarfism and various craniosynostosis syndromes affecting limb and craniofacial bone patterning. A functional analysis of several of these mutations has demonstrated that a constitutive activation of the receptor kinase is a common theme.

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http://dx.doi.org/10.1016/s0959-437x(97)80152-9DOI Listing

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