The expanding boundaries of sphingolipid lysosomal storage diseases; insights from Niemann-Pick disease type C.

Biochem Soc Trans

Department of Pharmacology, University of Oxford, Mansfield Road, Oxford OX1 3QT, U.K.

Published: October 2023

Lysosomal storage diseases are inborn errors of metabolism that arise due to loss of function mutations in genes encoding lysosomal enzymes, protein co-factors or lysosomal membrane proteins. As a consequence of the genetic defect, lysosomal function is impaired and substrates build up in the lysosome leading to 'storage'. A sub group of these disorders are the sphingolipidoses in which sphingolipids accumulate in the lysosome. In this review, I will discuss how the study of these rare lysosomal disorders reveals unanticipated links to other rare and common human diseases using Niemann-Pick disease type C as an example.

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Source
http://www.ncbi.nlm.nih.gov/pmc/articles/PMC10657176PMC
http://dx.doi.org/10.1042/BST20220711DOI Listing

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