AI Article Synopsis

  • Hereditary transthyretin (ATTRv) amyloidosis is an autosomal dominant disorder caused by mutations in the transthyretin gene, leading to a range of symptoms due to amyloid deposits affecting various organs.
  • The review highlights best practices from amyloidosis centers in Japan, Brazil, and Portugal, mainly focusing on managing asymptomatic gene mutation carriers and assessing their health through specific noninvasive tests and biopsies.
  • It emphasizes the need for regular monitoring (every 6 to 12 months) of patients' overall health and functional status, along with developing robust referral networks for better patient management in both endemic and non-endemic regions.

Article Abstract

Hereditary transthyretin (ATTRv) amyloidosis is a rare and autosomal dominant disorder associated with mutations in the transthyretin gene. Patients present with diverse symptoms related to sensory, motor, and autonomic neuropathy, as well as gastrointestinal, ocular, cardiac, renal and orthopedic symptoms, resulting from the deposition of transthyretin amyloid fibrils in multiple organs. The progressive nature of ATTRv amyloidosis necessitates pre- and post-onset monitoring of the disease. This review article is primarily based on a collation of discussions from a medical advisory board meeting in August 2021. In this article, we summarize the best practices in amyloidosis centers in three major endemic countries for ATTRv amyloidosis (Japan, Brazil, and Portugal), where most patients carry the Val30Met mutation in the transthyretin gene and the patients' genetic background was proven to be the same. The discussions highlighted the similarities and differences in the management of asymptomatic gene mutation carriers among the three countries in terms of the use of noninvasive tests and tissue biopsies and timing of starting the investigations. In addition, this article discusses a set of practical tests and examinations for monitoring disease progression applicable to neurologists working in diverse medical settings and generalizable in non-endemic countries and areas. This set of assessments consists of periodic (every 6 to 12 months) evaluations of patients' nutritional status and autonomic, renal, cardiac, ophthalmologic, and neurological functions. Physical examinations and patient-reported outcome assessments should be also scheduled every 6 to 12 months. Programs for monitoring gene mutation carriers and robust referral networks can aid in appropriate patient management in pre- to post-onset stages. For pre- and post-symptom onset testing for ATTRv amyloidosis, various noninvasive techniques are available; however, their applicability differs depending on the medical setting in each country and region, and the optimal option should be selected in view of the clinical settings, medical environment, and available healthcare resources in each region.

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Source
http://www.ncbi.nlm.nih.gov/pmc/articles/PMC10571420PMC
http://dx.doi.org/10.1186/s13023-023-02910-3DOI Listing

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