The link between rheumatic disorders and inborn errors of immunity.

EBioMedicine

Department of Rheumatology and Immunology, Hannover Medical University, Hannover, Germany; Hannover Medical School, Cluster of Excellence RESIST (EXC 2155), Hannover, Germany.

Published: April 2023

AI Article Synopsis

  • Inborn errors of immunity (IEIs) are genetic immunological disorders that lead to various issues like increased susceptibility to infections, immune dysfunction, and sometimes cancers due to mutations in single genes.
  • Many of these disorders, initially recognized for severe infections, also present with symptoms like autoimmunity or autoinflammation as key signs.
  • The review discusses recent IEIs associated with autoimmune conditions, their underlying mechanisms, and their potential implications for understanding systemic rheumatic diseases.

Article Abstract

Inborn errors of immunity (IEIs) are immunological disorders characterized by variable susceptibility to infections, immune dysregulation and/or malignancies, as a consequence of damaging germline variants in single genes. Though initially identified among patients with unusual, severe or recurrent infections, non-infectious manifestations and especially immune dysregulation in the form of autoimmunity or autoinflammation can be the first or dominant phenotypic aspect of IEIs. An increasing number of IEIs causing autoimmunity or autoinflammation, including rheumatic disease have been reported over the last decade. Despite their rarity, identification of those disorders provided insight into the pathomechanisms of immune dysregulation, which may be relevant for understanding the pathogenesis of systemic rheumatic disorders. In this review, we present novel IEIs primarily causing autoimmunity or autoinflammation along with their pathogenic mechanisms. In addition, we explore the likely pathophysiological and clinical relevance of IEIs in systemic rheumatic disorders.

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Source
http://www.ncbi.nlm.nih.gov/pmc/articles/PMC9996386PMC
http://dx.doi.org/10.1016/j.ebiom.2023.104501DOI Listing

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