Mitochondrial myopathy associated with a novel mutation in mtDNA.

Neuromuscul Disord

Dept. of Neurology, H. Houston Merritt Clinical Research Center for Muscular Dystrophy and Related Diseases, Columbia University Medical Center, 630 W. 168th Street, New York, NY 10032, USA.

Published: August 2007

A 6-year-old boy had progressive muscle weakness since age 4 and emotional problems diagnosed as Asperger syndrome. His mother and two older siblings are in good health and there is no family history of neuromuscular disorders. Muscle biopsy showed ragged-red and cytochrome coxidase (COX)-negative fibers. Respiratory chain activities were reduced for all enzymes containing mtDNA-encoded subunits, especially COX. Sequence analysis of the 22 tRNA genes revealed a novel G10406A base substitution, which was heteroplasmic in multiple tissues of the patient by RFLP analysis (muscle, 96%; urinary sediment, 94%; cheek mucosa, 36%; blood, 29%). The mutation was not detected in any accessible tissues from his mother or siblings. It appears that this mutation arose de novo in the proband, probably early in embryogenesis.

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http://www.ncbi.nlm.nih.gov/pmc/articles/PMC2699619PMC
http://dx.doi.org/10.1016/j.nmd.2007.04.005DOI Listing

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