Characterization of sequences and mechanisms through which ISE/ISS-3 regulates FGFR2 splicing.

Nucleic Acids Res

Department of Medicine, University of Pennsylvania School of Medicine, 700 Clinical Research Building, 415 Curie Blvd., Philadelphia, PA 19104, USA.

Published: January 2006

AI Article Synopsis

Article Abstract

Alternative splicing of fibroblast growth factor receptor-2 (FGFR2) mutually exclusive exons IIIb and IIIc results in highly cell-type-specific expression of functionally distinct receptors, FGFR2-IIIb and FGFR2-IIIc. We previously identified an RNA cis-element, ISE/ISS-3, that enhanced exon IIIb splicing and silenced exon IIIc splicing. Here, we have performed comprehensive mutational analysis to define critical sequence motifs within this element that independently either enhance splicing of upstream exons or repress splicing of downstream exons. Such analysis included use of a novel fluorescence-based splicing reporter assay that allowed quantitative determination of relative functional activity of ISE/ISS-3 mutants using flow cytometric analysis of live cells. We determined that specific sequences within this element that mediate splicing enhancement also mediate splicing repression, depending on their position relative to a regulated exon. Thus, factors that bind the element are likely to be coordinately involved in mediating both aspects of splicing regulation. Exon IIIc silencing is dependent upon a suboptimal branchpoint sequence containing a guanine branchpoint nucleotide. Previous studies of exon IIIc splicing in HeLa nuclear extracts demonstrated that this guanine branchsite primarily impaired the second step of splicing suggesting that ISE/ISS-3 may block exon IIIc inclusion at this step. However, results presented here that include use of newly developed in vitro splicing assays of FGFR2 using extracts from a cell line expressing FGFR2-IIIb strongly suggest that cell-type-specific silencing of exon IIIc occurs at or prior to the first step of splicing.

Download full-text PDF

Source
http://www.ncbi.nlm.nih.gov/pmc/articles/PMC1331989PMC
http://dx.doi.org/10.1093/nar/gkj407DOI Listing

Publication Analysis

Top Keywords

exon iiic
20
splicing
14
iiic splicing
8
mediate splicing
8
step splicing
8
exon
7
iiic
6
characterization sequences
4
sequences mechanisms
4
ise/iss-3
4

Similar Publications

Biallelic variants in GTF3C3 result in an autosomal recessive disorder with intellectual disability.

Genet Med

January 2025

School of Health, University of the Sunshine Coast, Maroochydore, QLD, Australia; National PTSD Research Centre, Thompson Institute, Birtinya, QLD, Australia. Electronic address:

Article Synopsis
  • This study identifies a new type of autosomal recessive intellectual disability linked to genetic variants in the GTF3C3 gene, which is essential for proper RNA polymerase III activity.
  • Researchers employed various methods, including exome sequencing and Drosophila models, to analyze the effects of GTF3C3 variants found in twelve affected individuals from seven families.
  • The results showed that the variants lead to significant functional losses in the gene, correlating with symptoms like intellectual disability, motor issues, seizures, and brain structure abnormalities.
View Article and Find Full Text PDF

Background: Hereditary diffuse gastric cancer (HDGC) (OMIM# 137215) is an autosomal dominant cancer syndrome associated with CDH1 (OMIM# 192090) mutations. Prophylactic total gastrectomy (PTG) is the most recommended preventive treatment when a pathogenic mutation is found. However, the increasing use of genetic testing has led to the identification of incidental CDH1 mutations in individuals without a family history of gastric cancer.

View Article and Find Full Text PDF

Case Report: From epilepsy and uterus didelphys to Turner syndrome-associated dysgerminoma.

Front Genet

January 2024

Department of Obstetrics and Gynecology, Beijing Tiantan Hospital, Capital Medical University, Beijing, China.

Dysgerminoma is a rare occurrence in Turner syndrome patients without Y chromosome mosaicism or hormone therapy during puberty. We present a unique case of a 33-year-old nulliparous Chinese woman with intermittent epilepsy and Mullerian anomalies carrying a double uterus, cervix, and vagina. The patient is also characterized as having Turner syndrome accompanied by 46,X, del(Xp22.

View Article and Find Full Text PDF
Article Synopsis
  • In rare cases, extensive DM in young children can indicate the presence of mucopolysaccharidoses (MPS), specifically linked to conditions like Hurler syndrome and Hunter syndrome.
  • A new case study involving a two-year-old boy suggests a potential connection between extensive congenital DM and MPS type IIIC, raising questions about mild phenotypic expressions in carriers of lysosomal storage disorders (LySD).
View Article and Find Full Text PDF
Article Synopsis
  • Befotertinib is a new type of medicine for lung cancer that targets specific mutations in patients' cells.
  • A study tested how well befotertinib worked compared to another medicine called icotinib in people with advanced lung cancer.
  • The study involved 362 patients and showed that people taking befotertinib had a longer time before their cancer got worse compared to those taking icotinib.
View Article and Find Full Text PDF

Want AI Summaries of new PubMed Abstracts delivered to your In-box?

Enter search terms and have AI summaries delivered each week - change queries or unsubscribe any time!