Kyrieleis like plaques - atypical presentation of ocular Behcet's disease.

To report an unusual presentation with kyrieleis like plaques in a patient with ocular Behcet's disease. A 28-year-old young male presented with blurring of vision in the left eye, fundus examination revealing focal segmental intra-arterial plaques involving all branches of retinal artery characteristics of kyrieleis-like plaques with no features of retinitis in retinal periphery and mild vitritis. All routine investigations were normal, the patient testing positive for HLA-B51 marker, diagnosed as a case of ocular Bechet's disease and managed with oral steroids and immunosuppressive agents.